Gitelman syndrome with a novel frameshift variant in SLC12A3 gene accompanied by chronic kidney disease and type 2 diabetes mellitus.


Journal

CEN case reports
ISSN: 2192-4449
Titre abrégé: CEN Case Rep
Pays: Japan
ID NLM: 101636244

Informations de publication

Date de publication:
05 2022
Historique:
received: 27 07 2021
accepted: 28 09 2021
pubmed: 8 10 2021
medline: 6 5 2022
entrez: 7 10 2021
Statut: ppublish

Résumé

Gitelman syndrome is an autosomal recessive genetic disease caused by pathogenic variants in SLC12A3 resulting in the loss of function of the Na-Cl co-transporter (NCC) in the distal tubules. Hypokalemia and diuretic effects can cause secondary type 2 diabetes and renal function decline. Here, we present the case of a 49-year-old male patient with chronic persistent treatment-resistant hypokalemia for the past 13 years who had been receiving treatment for type 2 diabetes mellitus for 6 years. He was referred to our department due to the presence of urinary protein, impaired renal function, high renin activity, and hyperaldosteronism. Laboratory test results showed hypokalemia, hypomagnesemia, hypocalciuria, and metabolic alkalosis. Using next-generation and Sanger sequencing, we identified a novel stop-gain variant (NM_000339.3:c.137del [p.His47fs]) and a missense variant (NM_000339.3:c.2927C > T [p.Ser976Phe]) in the SLC12A3 gene. This novel pathogenic variant was located at the intracellular N-terminus of the NCC. Based on these findings, the patient was diagnosed with Gitelman syndrome. The use of next-generation sequencing facilitated the exclusion of diseases with similar clinical symptoms.

Identifiants

pubmed: 34617250
doi: 10.1007/s13730-021-00652-4
pii: 10.1007/s13730-021-00652-4
pmc: PMC9061911
doi:

Substances chimiques

SLC12A3 protein, human 0
Solute Carrier Family 12, Member 3 0

Types de publication

Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

191-195

Informations de copyright

© 2021. Japanese Society of Nephrology.

Références

QJM. 2011 Nov;104(11):939-44
pubmed: 21705784
J Cell Sci. 2016 Feb 1;129(3):461-7
pubmed: 26787741
Kidney Int. 2017 Jan;91(1):24-33
pubmed: 28003083
Kidney Int. 2019 Aug;96(2):302-319
pubmed: 31133455
J Hum Genet. 2017 Feb;62(2):335-337
pubmed: 27784896
J Am Soc Nephrol. 2019 Aug;30(8):1534-1545
pubmed: 31285285
Genet Med. 2015 May;17(5):405-24
pubmed: 25741868
Am J Nephrol. 2013;37(2):152-7
pubmed: 23392128
BMC Nephrol. 2018 Oct 19;19(1):275
pubmed: 30340552
Hum Mutat. 2010 Dec;31(12):1304-15
pubmed: 20848653
Hypertension. 2006 Aug;48(2):219-24
pubmed: 16801488
Clin Kidney J. 2018 Jun;11(3):302-309
pubmed: 29942493
Nephrol Dial Transplant. 2013 Jun;28(6):1533-42
pubmed: 23328711
Nephrol Dial Transplant. 2014 Sep;29 Suppl 4:iv117-20
pubmed: 25165177
Kidney Int. 2018 Feb;93(2):325-334
pubmed: 29276100
J Clin Endocrinol Metab. 2012 Aug;97(8):E1478-82
pubmed: 22679066
J Korean Med Sci. 2016 Jan;31(1):47-54
pubmed: 26770037
J Am Soc Nephrol. 2011 Apr;22(4):693-703
pubmed: 21415153
Medicine (Baltimore). 2020 Jul 17;99(29):e21123
pubmed: 32702863
Hum Mutat. 2021 Mar;42(3):300-309
pubmed: 33348466
Clin Exp Nephrol. 2017 Feb;21(1):63-75
pubmed: 26920127
Eur J Hum Genet. 2012 Mar;20(3):263-70
pubmed: 22009145

Auteurs

Kenichiro Iio (K)

Department of Nephrology, National Hospital Organization Osaka Minami Medical Center, 2-1 Kidohigashimachi, Kawachinagano, Osaka, 586-8521, Japan. iioken16@outlook.com.

Takayasu Mori (T)

Department of Nephrology, Graduate School of Medical and Dental Sciences, Tokyo Medical and Dental University, 1-5-45 Yushima, Bunkyo-ku, Tokyo, 113-8510, Japan.

Saki Bessho (S)

Department of Nephrology, National Hospital Organization Osaka Minami Medical Center, 2-1 Kidohigashimachi, Kawachinagano, Osaka, 586-8521, Japan.

Yosuke Imai (Y)

Department of Nephrology, National Hospital Organization Osaka Minami Medical Center, 2-1 Kidohigashimachi, Kawachinagano, Osaka, 586-8521, Japan.

Masaki Hatanaka (M)

Department of Nephrology, National Hospital Organization Osaka Minami Medical Center, 2-1 Kidohigashimachi, Kawachinagano, Osaka, 586-8521, Japan.

Hiroki Omori (H)

Department of Nephrology, National Hospital Organization Osaka Minami Medical Center, 2-1 Kidohigashimachi, Kawachinagano, Osaka, 586-8521, Japan.

Haruhiko Kouhara (H)

Department of Endocrinology and Metabolism, Osaka Minami Medical Center, 2-1 Kidohigashimachi, Kawachinagano, Osaka, 586-8521, Japan.

Motoko Chiga (M)

Department of Nephrology, Graduate School of Medical and Dental Sciences, Tokyo Medical and Dental University, 1-5-45 Yushima, Bunkyo-ku, Tokyo, 113-8510, Japan.

Eisei Sohara (E)

Department of Nephrology, Graduate School of Medical and Dental Sciences, Tokyo Medical and Dental University, 1-5-45 Yushima, Bunkyo-ku, Tokyo, 113-8510, Japan.

Shinichi Uchida (S)

Department of Nephrology, Graduate School of Medical and Dental Sciences, Tokyo Medical and Dental University, 1-5-45 Yushima, Bunkyo-ku, Tokyo, 113-8510, Japan.

Jun-Ya Kaimori (JY)

Department of Inter-Organ Communication Research in Kidney Disease, Osaka University Graduate School of Medicine, 2-2 Yamadaoka, Suita, 565-0871, Japan.

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Classifications MeSH