The role of the electrocardiographic phenotype in risk stratification for sudden cardiac death in childhood hypertrophic cardiomyopathy.


Journal

European journal of preventive cardiology
ISSN: 2047-4881
Titre abrégé: Eur J Prev Cardiol
Pays: England
ID NLM: 101564430

Informations de publication

Date de publication:
30 03 2022
Historique:
received: 04 01 2021
revised: 25 02 2021
accepted: 09 03 2021
pubmed: 28 3 2021
medline: 2 4 2022
entrez: 27 3 2021
Statut: ppublish

Résumé

The 12-lead electrocardiogram (ECG) is routinely performed in children with hypertrophic cardiomyopathy (HCM). An ECG risk score has been suggested as a useful tool for risk stratification, but this has not been independently validated. This aim of this study was to describe the ECG phenotype of childhood HCM in a large, international, multi-centre cohort and investigate its role in risk prediction for arrhythmic events. Data from 356 childhood HCM patients with a mean age of 10.1 years (±4.5) were collected from a retrospective, multi-centre international cohort. Three hundred and forty-seven (97.5%) patients had ECG abnormalities at baseline, most commonly repolarization abnormalities (n = 277, 77.8%); left ventricular hypertrophy (n = 240, 67.7%); abnormal QRS axis (n = 126, 35.4%); or QT prolongation (n = 131, 36.8%). Over a median follow-up of 3.9 years (interquartile range 2.0-7.7), 25 (7%) had an arrhythmic event, with an overall annual event rate of 1.38 (95% CI 0.93-2.04). No ECG variables were associated with 5-year arrhythmic event on univariable or multivariable analysis. The ECG risk score threshold of >5 had modest discriminatory ability [C-index 0.60 (95% CI 0.484-0.715)], with corresponding negative and positive predictive values of 96.7% and 6.7. In a large, international, multi-centre cohort of childhood HCM, ECG abnormalities were common and varied. No ECG characteristic, either in isolation or combined in the previously described ECG risk score, was associated with 5-year sudden cardiac death risk. This suggests that the role of baseline ECG phenotype in improving risk stratification in childhood HCM is limited.

Identifiants

pubmed: 33772274
pii: 6190935
doi: 10.1093/eurjpc/zwab046
pmc: PMC8967480
doi:

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

645-653

Subventions

Organisme : British Heart Foundation
ID : FS/16/72/32270
Pays : United Kingdom
Organisme : Medical Research Council
ID : MR/T024062/1
Pays : United Kingdom
Organisme : Department of Health
Pays : United Kingdom

Informations de copyright

© The Author(s) 2021. Published by Oxford University Press on behalf of the European Society of Cardiology.

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Auteurs

Gabrielle Norrish (G)

Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK.
Institute of Cardiovascular Sciences, University College London, London, UK.

Cristian Topriceanu (C)

Institute of Cardiovascular Sciences, University College London, London, UK.

Chen Qu (C)

Department of Statistical Science, University College London, London, UK.

Ella Field (E)

Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK.
Institute of Cardiovascular Sciences, University College London, London, UK.

Helen Walsh (H)

Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK.

Lidia Ziółkowska (L)

Department of Cardiology, The Children's Memorial Health Institute, Warsaw, Poland.

Iacopo Olivotto (I)

Careggi University Hospital, Florence, Italy.

Silvia Passantino (S)

Cardiology Unit, A Meyer Pediatric Hospital, Florence, Italy.

Silvia Favilli (S)

Cardiology Unit, A Meyer Pediatric Hospital, Florence, Italy.

Aris Anastasakis (A)

Onassis Cardiac Surgery Center, Athens, Greece.

Vasiliki Vlagkouli (V)

Onassis Cardiac Surgery Center, Athens, Greece.

Robert Weintraub (R)

The Royal Children's Hospital, Melbourne, Australia.
The Murdoch Children's Research Institute.
University of Melbourne, Australia.

Ingrid King (I)

The Murdoch Children's Research Institute.

Elena Biagini (E)

S. Orsola-Malpighi Hospital, Bologna, Italy.

Luca Ragni (L)

S. Orsola-Malpighi Hospital, Bologna, Italy.

Terrence Prendiville (T)

Our Lady's Children's Hospital, Dublin, Ireland.

Sophie Duignan (S)

Our Lady's Children's Hospital, Dublin, Ireland.

Karen McLeod (K)

Royal Hospital for Children, Glasgow, UK.

Maria Ilina (M)

Royal Hospital for Children, Glasgow, UK.

Adrian Fernández (A)

Favaloro Foundation University Hospital, Buenos Aires, Argentina.

Regina Bökenkamp (R)

Leiden University Medical Center, Leiden, Netherlands.

Anwar Baban (A)

Bambino Gesu Hospital, Rome, Italy.

Fabrizio Drago (F)

Bambino Gesu Hospital, Rome, Italy.

Peter Kubuš (P)

University Hospital Motol, Prague, Czech Republic.

Piers E F Daubeney (PEF)

Royal Brompton and Harefield NHS Trust, London, UK.

Sian Chivers (S)

Royal Brompton and Harefield NHS Trust, London, UK.

Georgia Sarquella-Brugada (G)

Arrhythmia and Inherited Cardiac Diseases Unit, Hospital Sant Joan de Déu, University of Barcelona, Spain.
Medical Sciences Department, School of Medicine, University of Girona.

Sergi Cesar (S)

Arrhythmia and Inherited Cardiac Diseases Unit, Hospital Sant Joan de Déu, University of Barcelona, Spain.

Chiara Marrone (C)

Papa Giovanni XXIII hospital, Bergamo, Italy.

Constancio Medrano (C)

Hospital General Universitario Gregorio Marañón, Madrid, Spain.

Reyes Alvarez Garcia-Roves (R)

Hospital General Universitario Gregorio Marañón, Madrid, Spain.

Orhan Uzun (O)

University Hospital of Wales, Cardiff, UK.

Ferran Gran (F)

Val d'Hebron University Hospital, Barcelona, Spain.

Fernandez J Castro (FJ)

University Hospital Virgen de la Arrixaca, Murcia, Spain.

Juan R Gimeno (JR)

University Hospital Virgen de la Arrixaca, Murcia, Spain.

Roberto Barriales-Villa (R)

Complexo Hospitalario Universitario A Coruña, CIBERCV, A Coruña, Spain.

Fernando Rueda (F)

Complexo Hospitalario Universitario A Coruña, CIBERCV, A Coruña, Spain.

Satish Adwani (S)

John Radcliffe Hospital, Oxford, UK.

Jonathan Searle (J)

John Radcliffe Hospital, Oxford, UK.

Tara Bharucha (T)

Southampton general Hospital, Southampton, UK.

Ana Siles (A)

Hospital Universitario Puerta de Hierro Majadahonda, CIBERCV, Madrid, Spain.
University Francisco de Vitoria, Pozuelo de Alarcon, Spain.

Ana Usano (A)

Hospital Universitario Puerta de Hierro Majadahonda, CIBERCV, Madrid, Spain.
University Francisco de Vitoria, Pozuelo de Alarcon, Spain.

Torsten B Rasmussen (TB)

Department of cardiology, Aarhus University Hospital, Aarhus, Denmark.

Caroline B Jones (CB)

Alder Hey Children's hospital, Liverpool, UK.

Toru Kubo (T)

Department of Cardiology and Geriatrics, Kochi Medical School, Kochi University, Japan.

Jens Mogensen (J)

Odense University Hospital, Odense, Denmark.

Zdenka Reinhardt (Z)

The Freeman Hospital, Newcastle, UK.

Elena Cervi (E)

Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK.
Institute of Cardiovascular Sciences, University College London, London, UK.

Perry M Elliott (PM)

Institute of Cardiovascular Sciences, University College London, London, UK.
St Bartholomew's Centre for Inherited Cardiovascular Diseases, St Bartholomew's Hospital, West Smithfield, London, UK.

Rumana Z Omar (RZ)

Department of Statistical Science, University College London, London, UK.

Juan P Kaski (JP)

Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK.
Institute of Cardiovascular Sciences, University College London, London, UK.

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