Unveiling the Uncommon: A Unique Case of ALPS-Like Syndrome Complicated by Plasma Cell Disorder.


Journal

Journal of pediatric hematology/oncology
ISSN: 1536-3678
Titre abrégé: J Pediatr Hematol Oncol
Pays: United States
ID NLM: 9505928

Informations de publication

Date de publication:
23 Apr 2024
Historique:
received: 26 11 2023
accepted: 14 03 2024
medline: 23 4 2024
pubmed: 23 4 2024
entrez: 23 4 2024
Statut: aheadofprint

Résumé

Multiple myeloma is a rare disease in pediatrics, where about 30 cases are described under 15 years old. It is even rarer when atypical multiple myeloma occurs in the context of autoimmunity. This case describes a 9-year-old female with autoimmune lymphoproliferative-like disease and combined immune deficiency that developed acute kidney failure with monoclonal peak associated with RAC2 and TNFRSF9 variants. An adapted protocol from the backbone adult multiple myeloma standard of care with the addition of an allogeneic hematopoietic stem cell transplant was used. The patient, now nearly a year posttransplant, shows 100% chimerism with no sign of relapse.

Identifiants

pubmed: 38652075
doi: 10.1097/MPH.0000000000002859
pii: 00043426-990000000-00403
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

Copyright © 2024 Wolters Kluwer Health, Inc. All rights reserved.

Déclaration de conflit d'intérêts

The authors declare no conflicts of interest.

Références

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Auteurs

Meziane Brizini (M)

Department of Pediatrics, CHU de Québec, Université Laval.

Bruno Michon (B)

Department of Pediatrics Hematology-Oncology, CHU de Québec, Université Laval.

Marc-Antoine Bédard (MA)

Department of Immunology and Allergy, CHU de Québec, Université Laval, Québec, Canada.

Classifications MeSH