Serum glial fibrillary acidic protein and disability progression in progressive multiple sclerosis.


Journal

Annals of clinical and translational neurology
ISSN: 2328-9503
Titre abrégé: Ann Clin Transl Neurol
Pays: United States
ID NLM: 101623278

Informations de publication

Date de publication:
19 Dec 2023
Historique:
revised: 29 10 2023
received: 27 09 2023
accepted: 21 11 2023
medline: 19 12 2023
pubmed: 19 12 2023
entrez: 19 12 2023
Statut: aheadofprint

Résumé

Progression prediction is a significant unmet need in people with progressive multiple sclerosis (pwPMS). Studies on glial fibrillary acidic protein (GFAP) have either been limited to single center with relapsing MS or were based solely on Expanded Disability Status Scale (EDSS), which limits its generalizability to state-of-the-art clinical settings and trials applying combined outcome parameters. Serum GFAP and NfL (neurofilament light chain) were investigated in EmBioProMS participants with primary (PP) or secondary progressive MS. Six months confirmed disability progression (CDP) was defined using combined outcome parameters (EDSS, timed-25-foot walk test (T25FW), and nine-hole-peg-test (9HPT)). 243 subjects (135 PPMS, 108 SPMS, age 55.5, IQR [49.7-61.2], 135 female, median follow-up: 29.3 months [17.9-40.9]) were included. NfL (age-) and GFAP (age- and sex-) adjusted Z scores were higher in pwPMS compared to HC (p < 0.001 for both). 111 (32.8%) CDP events were diagnosed in participants with ≥3 visits (n = 169). GFAP Z score >3 was associated with higher risk for CDP in participants with low NfL Z score (i.e., ≤1.0) (HR: 2.38 [1.12-5.08], p = 0.025). In PPMS, GFAP Z score >3 was associated with higher risk for CDP (HR: 2.88 [1.21-6.84], p = 0.016). Risk was further increased in PPMS subjects with high GFAP when NfL is low (HR: 4.31 [1.53-12.13], p = 0.006). Blood GFAP may help identify pwPPMS at risk of progression. Combination of high GFAP and low NfL levels could distinguish non-active pwPMS with particularly high progression risk.

Identifiants

pubmed: 38111972
doi: 10.1002/acn3.51969
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Aktion Multiple Sklerose Erkrankter Landesverband (AMSEL)
Organisme : Bayerische MS-Stiftung
Organisme : Deutschen Multiple Sklerose Gesellschaft

Informations de copyright

© 2023 The Authors. Annals of Clinical and Translational Neurology published by Wiley Periodicals LLC on behalf of American Neurological Association.

Références

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Auteurs

Ahmed Abdelhak (A)

Department of Neurology, University of California San Francisco (UCSF), San Francisco, California, USA.
Department of Neurology, University Hospital of Ulm, Ulm, Germany.

Kai Antweiler (K)

Department of Medical Statistics, University Medical Centre Göttingen, Göttingen, Germany.

Markus C Kowarik (MC)

Department of Neurology and Stroke, University Hospital of Tübingen, Tübingen, Germany.
Hertie Institute for Clinical Brain Research, University of Tübingen, Tübingen, Germany.

Makbule Senel (M)

Department of Neurology, University Hospital of Ulm, Ulm, Germany.

Joachim Havla (J)

Institute of Clinical Neuroimmunology, LMU Hospital, Ludwig-Maximilians University, Munich, Germany.

Uwe K Zettl (UK)

Department of Neurology, Neuroimmunological Section, University of Rostock, Rostock, Germany.

Ingo Kleiter (I)

Marianne-Strauß-Klinik, Behandlungszentrum Kempfenhausen für Multiple Sklerose Kranke gGmbH, Berg, Germany.

Thomas Skripuletz (T)

Department of Neurology, Hannover Medical School, Hanover, Germany.

Axel Haarmann (A)

Department of Neurology, University Hospital Würzburg, Würzburg, Germany.

Alexander Stahmann (A)

Forschungs- und Projektentwicklungs-gGmbH, MS-Registry by the German MS-Society, Hanover, Germany.

Andre Huss (A)

Department of Neurology, University Hospital of Ulm, Ulm, Germany.

Stefan Gingele (S)

Department of Neurology, Hannover Medical School, Hanover, Germany.

Markus Krumbholz (M)

Department of Neurology and Stroke, University Hospital of Tübingen, Tübingen, Germany.
Hertie Institute for Clinical Brain Research, University of Tübingen, Tübingen, Germany.
Department of Neurology and Pain Treatment, Multiple Sclerosis Center, Center for Translational Medicine, Immanuel Klinik Rüdersdorf, University Hospital of the Brandenburg Medical School Theodor Fontane, Rüdersdorf bei Berlin, Germany.
Faculty of Health Sciences Brandenburg, Brandenburg Medical School Theodor Fontane, Rüdersdorf bei Berlin, Germany.

Pascal Benkert (P)

Multiple Sclerosis Centre and Research Center for Clinical Neuroimmunology and Neuroscience (RC2NB), Department of Biomedicine, University Hospital and University of Basel, Basel, Switzerland.
Multiple Sclerosis Centre and Research Center for Clinical Neuroimmunology and Neuroscience (RC2NB), Department of Clinical Research, University Hospital and University of Basel, Basel, Switzerland.
Department of Neurology, University Hospital and University of Basel, Basel, Switzerland.

Jens Kuhle (J)

Multiple Sclerosis Centre and Research Center for Clinical Neuroimmunology and Neuroscience (RC2NB), Department of Biomedicine, University Hospital and University of Basel, Basel, Switzerland.
Multiple Sclerosis Centre and Research Center for Clinical Neuroimmunology and Neuroscience (RC2NB), Department of Clinical Research, University Hospital and University of Basel, Basel, Switzerland.
Department of Neurology, University Hospital and University of Basel, Basel, Switzerland.

Tim Friede (T)

Department of Medical Statistics, University Medical Centre Göttingen, Göttingen, Germany.

Albert C Ludolph (AC)

Department of Neurology, University Hospital of Ulm, Ulm, Germany.
German Center for Neurodegenerative Diseases, Ulm, Germany.

Ulf Ziemann (U)

Department of Neurology and Stroke, University Hospital of Tübingen, Tübingen, Germany.
Hertie Institute for Clinical Brain Research, University of Tübingen, Tübingen, Germany.

Tania Kümpfel (T)

Institute of Clinical Neuroimmunology, LMU Hospital, Ludwig-Maximilians University, Munich, Germany.

Hayrettin Tumani (H)

Department of Neurology, University Hospital of Ulm, Ulm, Germany.

Classifications MeSH