Dynamic physiological α-synuclein S129 phosphorylation is driven by neuronal activity.


Journal

NPJ Parkinson's disease
ISSN: 2373-8057
Titre abrégé: NPJ Parkinsons Dis
Pays: United States
ID NLM: 101675390

Informations de publication

Date de publication:
16 Jan 2023
Historique:
received: 12 07 2022
accepted: 22 12 2022
entrez: 16 1 2023
pubmed: 17 1 2023
medline: 17 1 2023
Statut: epublish

Résumé

In Parkinson's disease and other synucleinopathies, the elevation of α-synuclein phosphorylated at Serine129 (pS129) is a widely cited marker of pathology. However, the physiological role for pS129 has remained undefined. Here we use multiple approaches to show for the first time that pS129 functions as a physiological regulator of neuronal activity. Neuronal activity triggers a sustained increase of pS129 in cultured neurons (200% within 4 h). In accord, brain pS129 is elevated in environmentally enriched mice exhibiting enhanced long-term potentiation. Activity-dependent α-synuclein phosphorylation is S129-specific, reversible, confers no cytotoxicity, and accumulates at synapsin-containing presynaptic boutons. Mechanistically, our findings are consistent with a model in which neuronal stimulation enhances Plk2 kinase activity via a calcium/calcineurin pathway to counteract PP2A phosphatase activity for efficient phosphorylation of membrane-bound α-synuclein. Patch clamping of rat SNCA

Identifiants

pubmed: 36646701
doi: 10.1038/s41531-023-00444-w
pii: 10.1038/s41531-023-00444-w
pmc: PMC9842642
doi:

Types de publication

Journal Article

Langues

eng

Pagination

4

Subventions

Organisme : NINDS NIH HHS
ID : R01 NS099328
Pays : United States
Organisme : NINDS NIH HHS
ID : RF1 NS122880
Pays : United States
Organisme : NINDS NIH HHS
ID : R01 NS109510
Pays : United States

Informations de copyright

© 2023. The Author(s).

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Auteurs

Nagendran Ramalingam (N)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA. nramalingam@bwh.harvard.edu.

Shan-Xue Jin (SX)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Tim E Moors (TE)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Luis Fonseca-Ornelas (L)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Kazuma Shimanaka (K)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Shi Lei (S)

Leveragen, Inc., 17 Briden Street, Worcester, MA, 01605, USA.

Hugh P Cam (HP)

Leveragen, Inc., 17 Briden Street, Worcester, MA, 01605, USA.

Aurelia Hays Watson (AH)

UK Dementia Research Institute, University College London, London, UK.

Lisa Brontesi (L)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Lai Ding (L)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Dinc Yasat Hacibaloglu (DY)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Haiyang Jiang (H)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Se Joon Choi (SJ)

Division of Molecular Therapeutics, New York State Psychiatric Institute, Research Foundation for Mental Hygiene, New York, NY, 10032, USA.

Ellen Kanter (E)

Division of Molecular Therapeutics, New York State Psychiatric Institute, Research Foundation for Mental Hygiene, New York, NY, 10032, USA.

Lei Liu (L)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Tim Bartels (T)

UK Dementia Research Institute, University College London, London, UK.

Silke Nuber (S)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

David Sulzer (D)

Division of Molecular Therapeutics, New York State Psychiatric Institute, Research Foundation for Mental Hygiene, New York, NY, 10032, USA.
Departments of Neurology and Psychiatry, Columbia University Medical Center, New York, NY, 10032, USA.
Department of Molecular Therapeutics and Pharmacology, Columbia University Medical Center, New York, NY, 10032, USA.

Eugene V Mosharov (EV)

Division of Molecular Therapeutics, New York State Psychiatric Institute, Research Foundation for Mental Hygiene, New York, NY, 10032, USA.
Departments of Neurology and Psychiatry, Columbia University Medical Center, New York, NY, 10032, USA.

Weisheng V Chen (WV)

Leveragen, Inc., 17 Briden Street, Worcester, MA, 01605, USA.

Shaomin Li (S)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Dennis J Selkoe (DJ)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA.

Ulf Dettmer (U)

Ann Romney Center for Neurologic Diseases, Brigham and Women's Hospital and Harvard Medical School, Boston, MA, 02115, USA. udettmer@bwh.harvard.edu.

Classifications MeSH