Diffuse cystic lung disease in sickle cell anaemia: a series of 22 cases and a case-control study.


Journal

Thorax
ISSN: 1468-3296
Titre abrégé: Thorax
Pays: England
ID NLM: 0417353

Informations de publication

Date de publication:
01 2022
Historique:
received: 28 12 2020
accepted: 20 05 2021
pubmed: 16 6 2021
medline: 3 2 2022
entrez: 15 6 2021
Statut: ppublish

Résumé

Chronic interstitial lung abnormalities have been described in sickle cell disease (SCD) and attributed to repetitive episode of acute chest syndrome. We report a series of 22 cases of diffuse cystic lung disease in SCD with a case-control study to hunt for mechanism. On pathological analysis of a surgical lung biopsy of the index case, the bronchioles had the appearance of constrictive bronchiolitis. Pulmonary function test results revealed lower forced expiratory flow from 25% to 75% of vital capacity in cases versus controls. These findings suggest a bronchiolar mechanism that was not associated with more acute chest syndrome.

Identifiants

pubmed: 34127555
pii: thoraxjnl-2020-216826
doi: 10.1136/thoraxjnl-2020-216826
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

91-93

Informations de copyright

© Author(s) (or their employer(s)) 2022. No commercial re-use. See rights and permissions. Published by BMJ.

Déclaration de conflit d'intérêts

Competing interests: None declared.

Auteurs

Fatma Kort (F)

Service de Pneumologie, Assistance Publique-Hôpitaux de Paris, Hôpital Tenon, Paris, France.

Anoosha Habibi (A)

French Sickle Cell Referral Center, Assistance Publique-Hôpitaux de Paris, Hôpital Henri Mondor, Creteil, France.
INSERM 955, Université Paris Est-Créteil, laboratoire d'excellence GR-Ex, Creteil, France.

Francois Lionnet (F)

Service de Médecine Interne, Assistance Publique-Hôpitaux de Paris, Hôpital Tenon, Paris, France.

Marie-France Carette (MF)

Service de Radiologie, Assistance Publique-Hôpitaux de Paris, Hôpital Tenon, Paris, France.

Antoine Parrot (A)

Service de Pneumologie, Assistance Publique-Hôpitaux de Paris, Hôpital Tenon, Paris, France.

Laurent Savale (L)

Service de Pneumologie, Assistance Publique-Hôpitaux de Paris, Hôpital Bicêtre, Le Kremlin-Bicêtre, France.

Hilario Nunes (H)

Service de Pneumologie, Assistance Publique Hôpitaux de Paris, Hôpital Avicenne, Bobigny, France.

Bernard Maitre (B)

Service de Pneumologie et de Pathologie Professionnelle, Centre Hospitalier Intercommunal de Créteil, Creteil, France.
DHU A-TVB, Université Paris Est-Créteil, Creteil, France.

Frederic Schlemmer (F)

Unité de Pneumologie, Assistance Publique-Hôpitaux de Paris, Hôpital Henri Mondor, Creteil, France.
INSERM 955, Université Paris Est-Créteil, Creteil, France.

Jean-Marc Naccache (JM)

Service de Pneumologie, Assistance Publique-Hôpitaux de Paris, Hôpital Tenon, Paris, France jmnaccache@ghpsj.fr.
Service de Pneumologie, Groupe Hospitalier Paris Saint Joseph, Paris, France.
Service de Pneumologie, Hôpital Foch, Suresnes, France.

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Classifications MeSH