Spectrum of peripheral retinal ischemia in Wyburn-Mason syndrome.

Arteriovenous malformation Central retinal vein occlusion Peripheral retinal ischemia Wyburn-mason syndrome

Journal

American journal of ophthalmology case reports
ISSN: 2451-9936
Titre abrégé: Am J Ophthalmol Case Rep
Pays: United States
ID NLM: 101679941

Informations de publication

Date de publication:
Jun 2020
Historique:
received: 30 01 2019
revised: 05 11 2019
accepted: 25 02 2020
entrez: 18 3 2020
pubmed: 18 3 2020
medline: 18 3 2020
Statut: epublish

Résumé

We report two cases of Wyburn-Mason syndrome that illustrate the spectrum of peripheral retinal ischemia seen in this condition. A 12-year-old female presented with a retinal arteriovenous malformation and sclerotic vessels associated with retinal ischemia on fluorescein angiography, as well as an ipsilateral ophthalmic arteriovenous malformation on magnetic resonance imaging. An 11-year-old male presented with retinal vascular engorgement and tortuosity along with a central retinal vein occlusion and secondary neovascularization. Retinal ischemia in Wyburn-Mason syndrome is heterogeneous and may be progressive, with secondary complications that result in neovascularization. Furthermore, it is necessary to recognize that this is a systemic condition that requires neurological evaluation.

Identifiants

pubmed: 32181415
doi: 10.1016/j.ajoc.2020.100640
pii: S2451-9936(19)30045-3
pii: 100640
pmc: PMC7063330
doi:

Types de publication

Case Reports

Langues

eng

Pagination

100640

Informations de copyright

© 2020 Published by Elsevier Inc.

Déclaration de conflit d'intérêts

Dr. Berrocal receives a consulting fee or honorarium from Alcon, and DORC, Allergan, Zeiss, Novartis, Visunex. The following authors have no financial disclosures: BF, JL, SP, CMS.

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Auteurs

Blake Fortes (B)

Florida International University, Herbert Wertheim College of Medicine Department of Ophthalmology, 11200 SW 8th Street, Miami, FL, 33199, USA.

James Lin (J)

Bascom Palmer Eye Institute, University of Miami Miller School of Medicine, Department of Ophthalmology, 900 NW 17th Street, Miami, FL, 33136, USA.

Supalert Prakhunhungsit (S)

Bascom Palmer Eye Institute, University of Miami Miller School of Medicine, Department of Ophthalmology, 900 NW 17th Street, Miami, FL, 33136, USA.

Carlos Mendoza-Santiesteban (C)

Bascom Palmer Eye Institute, University of Miami Miller School of Medicine, Department of Ophthalmology, 900 NW 17th Street, Miami, FL, 33136, USA.

Audina M Berrocal (AM)

Bascom Palmer Eye Institute, University of Miami Miller School of Medicine, Department of Ophthalmology, 900 NW 17th Street, Miami, FL, 33136, USA.

Classifications MeSH